Spontaneous hemothorax caused by a ruptured intercostal artery aneurysm in von Recklinghausen's neurofibromatosis

Wei Chou Chang, Hsian He Hsu, Hung Chang, Cheng Yu Chen

Research output: Contribution to journalArticle

11 Citations (Scopus)

Abstract

Aneurysms arising from an intercostal artery are very rare vascular malformations in von Recklinghausen's neurofibromatosis, which often have a silent clinical presentation and are difficult to diagnose before rupture. We report a case of von Recklinghausen's neurofibromatosis with massive hemothroax caused by spontaneous rupture of an intercostal artery aneurysm in a 29-year-old man. The diagnosis was eventually confirmed by percutaneous angiography and treated with endovascular embolization. During a 10-month follow-up period, the patient had a satisfactory recovery. This case illustrates that angiography and possible endovascular embolization should be the first strategy in managing hemothorax in patients with von Recklinghausen's disease.

Original languageEnglish
Pages (from-to)286-289
Number of pages4
JournalJournal of the Formosan Medical Association = Taiwan yi zhi
Volume104
Issue number4
Publication statusPublished - 2005
Externally publishedYes

Fingerprint

Hemothorax
Neurofibromatoses
Aneurysm
Angiography
Arteries
Vascular Malformations
Spontaneous Rupture
Neurofibromatosis 1
Rupture

Keywords

  • Aneurysm, ruptured
  • Embolization, therapeutic
  • Hemothorax
  • Neurofibromatosis 1
  • Thoracic arteries

ASJC Scopus subject areas

  • Medicine(all)

Cite this

Spontaneous hemothorax caused by a ruptured intercostal artery aneurysm in von Recklinghausen's neurofibromatosis. / Chang, Wei Chou; Hsu, Hsian He; Chang, Hung; Chen, Cheng Yu.

In: Journal of the Formosan Medical Association = Taiwan yi zhi, Vol. 104, No. 4, 2005, p. 286-289.

Research output: Contribution to journalArticle

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